Congenital oral synechia and ankyloblepharon filiforme adnatum: Case report and literature review

详细信息    查看全文

• 作者：Lí ; via Bonjardim Lima^a ; ^{liviabonjardim@hotmail.com" class="auth_mail" title="E-mail the corresponding author} ; Luiz Fernando Barbosa de Paulo^b ; Clá ; udia Jordã ; o Silva^c ; Vanessa Cristina Mendes^d ; Paulo Cé ; zar Simamoto-J&uacute ; nior^e ; Antô ; nio Francisco Durighetto^f (Jr)
• 关键词：Jaw abnormality ; Congenital defects ; Ectopic tissue ; Ankyloblepharon filiforme adnatum
• 刊名：International Journal of Pediatric Otorhinolaryngology
• 出版年：2016
• 出版时间：November 2016
• 年：2016
• 卷：90
• 期：Complete
• 页码：196-199
• 全文大小：605 K

文摘

Congenital intraoral synechias are adhesions of intraoral structures involving soft tissue. These conditions and another anomaly called ankyloblepharon filiforme adnatum, which is partial fusion of the eyelid margins by bands of tissue, are rarely reported in the literature. The association of both anomalies of the craniomaxillofacial region is an even more unusual finding.

Purpose

This article adds more information to the literature by reporting a case of a neonate with a rare association of bilateral synechia between the jaws, fusion of buccal mucosa to the ridges and between the tongue and palate, and ankyloblepharon filiforme adnatum in both eyes, without any other facial or systemic malformation.

Methods

A literature review of similar cases published in PUBMED/MEDLINE was conducted followed by a discussion and comparison to the new case.

Conclusion

The rare association of these congenital defects, without the presence of syndromic symptoms, could be diagnosed and treated easily with good prognostic evolution.